Lisha Sun

Intraosseous trigeminal schwannoma of mandible with intracranial extension

OBJECTIVE There have been few previous reports of intraosseous schwannomas within the mandible with extension into the cranium. We report two such cases and discuss the relevant clinical features, radiological manifestations and treatment protocols. METHOD Two case reports of trigeminal schwannoma of the mandible with intracranial extension, including analysis of clinical, radiological and pathological aspects. RESULTS Panoramic radiographs showed both tumours as multilocular radiolucencies. Solid and cystic components were seen on computed tomography and magnetic resonance imaging. The two tumours extended into the cranium through the pterygomandibular space and an obviously expanded foramen ovale. CONCLUSION Trigeminal schwannoma of the mandible can develop to involve intracranial extension. Radiological identification of an expanded foramen ovale may facilitate pre-operative identification.

Glial Choristoma in the Oral and Maxillofacial Region: A Clinicopathologic Study of 6 Cases

CONTEXT Glial choristoma is an uncommon developmental abnormality typically presenting at birth or in early childhood. The nasal region is most frequently affected. Palate, tongue, cheek, scalp, and orbit can also be affected but these occurrences are relatively rare. OBJECTIVE To report 6 cases of glial choristoma arising in the oral and maxillofacial region and to document the clinical and pathologic features of these lesions. DESIGN Histologic and immunocytochemical examinations were performed on 6 cases of glial choristoma. Biologic behavior, prognosis, and pathogenesis were discussed together with a review of the literature. RESULT The patients included 5 boys and 1 girl. They all presented with the lesions at birth or soon after birth. Four lesions occurred on the dorsal side of the tongue, near the foramen caecum. One lesion was present in the infratemporal fossa and parapharyngeal space, and the other one was in the submandibular region. All patients received surgical excision, and follow-up data revealed no recurrence for a period of 10 months to 5 years after surgery. Histologically, the lesions showed mature glial cells intermixed with connective tissue. The glial tissue was strongly positive for glial fibrillary acidic protein and S100 but negative for neurofilament. CONCLUSION Glial choristoma should be classified as a developmental malformation that occurs in many sites of the head and neck. In oral cavity, the tongue is the most frequently affected site. Although these lesions are rare, they should be included in the differential diagnosis of congenital masses in the oral and maxillofacial region.

Tooth abnormalities in congenital infiltrating lipomatosis of the face.

OBJECTIVE The aim of this study was to present a literature review and case series report of tooth abnormalities in congenital infiltrating lipomatosis of the face (CIL-F). METHODS Four typical cases of CIL-F are presented. Tooth abnormalities in CIL-F documented in the English literature are also reviewed. The clinical and radiological features of tooth abnormalities are summarized. RESULTS In total, 21 cases with tooth abnormalities in CIL-F were retrieved for analysis. Accelerated tooth formation and eruption (17 cases), macrodontia (9 cases), and root hypoplasia (8 cases) were observed in CIL-F. CONCLUSION Tooth abnormalities including accelerated tooth formation or eruption, macrodontia, and root hypoplasia are common in CIL-F.

Multiple complex odontoma of the maxilla and the mandible

OBJECTIVE The aim of this study was to present a literature review and case report of multiple odontoma. METHODS A case of multiple odontoma is presented with a review of the English-language literature. The clinical and radiologic features are summarized. RESULTS In total, 12 cases of multiple odontoma were retrieved from the literature for analysis. The multiple odontomas were localized or extensive and involved two to four quadrants of the jaws. The histologic types were compound or complex. CONCLUSION Odontomas can be multiple and involve multiple quadrants of the jaws.

Partial duplication of the mandible, parotid aplasia and facial cleft: a rare developmental disorder

Duplication deformity of the mandible is exceedingly rare. Its occurrence with congenital facial cleft and parotid gland aplasia has been rarely reported as 1 entity. We report such a case with detailed computed tomography (CT) description and provide a review of the literature on mandible duplication.

Congenital salivary fistula of an accessory parotid gland in Goldenhar syndrome.

OBJECTIVES We report two cases of congenital salivary fistula of an accessory parotid gland, and we discuss its occurrence in Goldenhar syndrome. METHODS Two teenagers complained of a congenital cheek fistula with constant salivary discharge. Computed tomography fistulography and sialography were performed. The diagnosis of Goldenhar syndrome was established based on clinical and imaging findings. Previously reported cases are reviewed and the clinical and radiological features summarised. RESULTS In these two patients, a salivary fistula of an accessory parotid gland was demonstrated on computed tomography fistulography, and did not communicate with Stensens duct. Deformity of Stensens duct and hypoplasia of the ipsilateral mandibular ramus were present. Tragal appendices have frequently been reported in such cases. CONCLUSION A congenital cheek salivary fistula of an accessory parotid gland should be considered indicative of Goldenhar syndrome.

Lingual dermoid cyst with congenital discharging sinus: a rare entity

OBJECTIVE There have been few reports of lingual dermoid cysts with a congenital discharging fistula. We report such a case, which mimicked lipoma on computed tomography, and we discuss relevant clinical and radiological features. METHOD We present a case report and a review of the English language literature concerning lingual dermoid cysts either mimicking lipoma or with a congenital discharging sinus. RESULTS A 35-year-old man presented with a lingual mass associated with a congenital fistula in the midline of the tongue dorsum, which discharged abnormal secretions. Computed tomography images showed that the lesion was well defined and contained homogeneous fatty tissue giving computed tomography attenuation values of -120 Hounsfield units. CONCLUSION Lingual dermoid cysts may develop with a midline discharging fistula, and may exhibit radiological similarity to lipomas on computed tomography.

Congenital parotid ectopia in accessory maxilla and facial cleft anomalies: Three cases report

To further document the clinical features of accessory maxilla with three additional cases report. Clinical and radiological features of three cases of accessory maxilla were presented. Related literature was summarized for comparison. Ectopic parotid gland, facial cleft and accessory maxilla are three concomitant malformations in this condition. The tooth-bearing accessory maxillary duplication derives from the abnormal growth of the zygoma or zygomatic arch. Facial cleft, parotid ectopia and tooth-bearing accessory maxilla may constitute a rare congenital syndrome.

Hypoplasia of the parotid gland: computed tomography sialography diagnosis

We report two unusual cases of non-syndromic hypoplasia of the parotid gland. The hypoplastic parotid gland mimicked a preauricular parotid tumor in one case and presented as an incidental image finding in the other case. Absence of the deep lobe and isthmus of the parotid parenchyma could be determined on axial computed tomography (CT) by revealing fat tissue composition of the parotid space. The underdeveloped superficial lobe of the gland was observed on three-dimensional CT sialography.

Intracranial arachnoid cyst on dental radiography: a diagnostic challenge

Intracranial arachnoid cysts (IACs) can present as congenital asymptomatic lesions that may predispose them to present as an incidental finding during radiographic examination. On the other hand, IACs may also give rise to a series of neurologic symptoms depending on their size and location, such as vomiting, seizures, headache, and ataxia. Skull deformities, including macrocephaly, may occur and become remarkable on dental radiology. We report 2 patients who were identified with IAC before orthodontic treatment. The dental radiologic appearance of IAC is discussed and may constitute a diagnostic challenge to both the dentist and radiologist.